Putaminal necrosis presenting with hemidystonia - 06/09/11
, Yoshihiro Takeuchi, MD , ⁎, Akiko Misawa, MD , Tadashi Sawada, MD , Yoshio Imahori, MD † Department of Pediatrics, Kyoto Prefectural University of Medicine, KyotoJapan Abstract |
A 7-year-old female presented with putaminal necrosis associated with hemidystonia. Cranial magnetic resonance imaging revealed bilateral putaminal lesions appearing as hypointense signals on T1-weighted images and hyperintense signals on T2-weighted images. After a differential diagnosis of basal ganglial degeneration was made, putaminal necrosis was diagnosed. Low doses of levodopa (0.5 mg/kg daily) were administered, but her clinical signs worsened. Positron emission tomography scanning with [18F]-6-fluoro-l-dopa revealed asymmetric uptake and right-sided dominant decreases of [18F]-6-fluoro-l-dopa uptake of the putamen. On the basis of these findings, standard doses of levodopa (10 mg/kg daily) were administered, and her clinical signs improved. These results suggest that hemidystonia is associated with a disturbance of the dopamine system.
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Vol 22 - N° 3
P. 222-224 - mars 2000 Retour au numéro
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